วันพฤหัสบดีที่ 26 กุมภาพันธ์ พ.ศ. 2569

Bleeding Disorder of Unknown Cause (BDUC)

Bleeding Disorder of Unknown Cause (BDUC)

1. Definition (Key concept)

BDUC (Bleeding Disorder of Unknown Cause) =
ภาวะเลือดออกผิดปกติทางคลินิก +
ผลตรวจ hemostasis มาตรฐาน “ปกติทั้งหมด”
หลัง exclusion ของ known bleeding disorders

เป็น diagnosis of exclusion เท่านั้น

ต้องมี:

  • Documented bleeding phenotype (เช่น BAT positive)
  • Normal comprehensive hemostatic testing

2. Diagnostic Criteria (Practical checklist)

วินิจฉัย BDUC เมื่อมี:

2.1 Clinical bleeding history +

2.2 Normal laboratory evaluation ครบ:

  • CBC + platelet count & morphology
  • PT / aPTT / thrombin time / fibrinogen
  • VWF antigen + activity (VWD panel)
  • Factor VIII, IX, XI activity
  • Platelet aggregation (gold standard)

⚠️ ไม่มี bleeding history ไม่เรียก BDUC แม้ lab ผิดปกติ


3. Epidemiology (High-yield)

  • พบใน 46–66% ของผู้ป่วยที่ส่ง consult bleeding tendency
  • Female predominance: 66–87%
  • อายุเฉลี่ยวินิจฉัย: 33–42 ปี
  • ~50% มี family history (มัก autosomal dominant pattern)

Clinical implication:

ผู้หญิงที่มี heavy menstrual bleeding + lab ปกติ = ต้องคิดถึง BDUC สูง


4. Pathophysiology (Current understanding)

ยังไม่ทราบสาเหตุชัดเจน
คาดว่าเป็น:

  • Polygenic low-penetrance variants
  • Mild platelet/vascular dysfunction ที่ตรวจไม่พบ
  • Undiscovered hemostatic disorders
  • Connective tissue fragility

5. Clinical Features (Pattern recognition)

5.1 Most common manifestations

เรียงจากพบบ่อย:

1.       Heavy menstrual bleeding (HMB) — สูงสุด (~90%)

2.       Mucocutaneous bleeding

o   Epistaxis

o   Gingival bleeding

o   Easy bruising

3.       Excessive surgical bleeding

4.       Postpartum hemorrhage (PPH)

Severity:

  • Comparable กับ mild VWD
  • 23% เคยต้อง transfusion (บาง cohort)

5.2 Associated complications

  • Iron deficiency (very common)
  • Iron deficiency anemia
  • Fatigue, RLS, hair loss, mood change

Clinical pearl:

Iron deficiency + unexplained bleeding = red flag ของ BDUC


6. Evaluation Framework (Stepwise approach for physicians)

STEP 1: Confirm “true abnormal bleeding”

ใช้:

ISTH-BAT (recommended)

Cut-off:

Group

Positive BAT

Child

3

Adult male

4

Adult female

5–6 (age dependent)

ข้อควรจำ:

  • BAT มี high NPV
  • Young patients อาจ BAT ต่ำเพราะไม่มี bleeding challenge

STEP 2: Detailed history (Critical)

ต้องถาม:

A. Bleeding challenges (high yield)

  • Surgery
  • Dental extraction
  • Delivery
  • Trauma

B. Menstrual history (สำคัญที่สุด)

  • Duration >7 days
  • Clots >2.5 cm
  • Flooding
  • Iron therapy need
  • PPH history

C. Family history

  • Bleeding
  • Iron deficiency anemia

D. Medication review

  • NSAIDs
  • SSRIs
  • Antiplatelets
  • Herbal supplements (ginkgo, vitamin E)

STEP 3: Exclude acquired causes ก่อน

ภาวะที่ mimic BDUC:

  • CKD (uremic platelet dysfunction)
  • Liver disease
  • Myeloproliferative neoplasm
  • Hypothyroidism
  • Alcohol use disorder

Clinical tip:

Treat underlying disease ก่อน extensive hematologic workup


7. Laboratory Evaluation to exclude specific disorders

7.1 Initial testing (all patients)

  • CBC + smear
  • PT / aPTT
  • Fibrinogen
  • VWD panel (VWF:Ag + activity)
  • Factor VIII, IX, XI
  • Platelet aggregation (if screening negative)

7.2 Additional testing (Selected cases)

Vitamin C level (often overlooked)

ควรพิจารณาใน:

  • Easy bruising
  • Hematoma
  • Malnutrition / restrictive diet
  • Post-bariatric surgery

Cutoff: <0.2 mg/dL scurvy
รักษาง่ายและ low risk


Factor XIII (important pitfall)

สงสัยเมื่อ:

  • Delayed bleeding
  • Normal PT/aPTT
  • Poor wound healing
  • Umbilical stump bleeding (history)

Hyperfibrinolysis testing

คิดถึงเมื่อ:

  • Delayed post-op bleeding
  • Normal routine labs
  • Severe unexplained bleeding

Tests:

  • D-dimer
  • ECLT (Euglobulin clot lysis time)
  • Fibrinogen trends

Chromogenic FVIII assay

สำคัญใน:

  • Suspected mild hemophilia A
  • Female carriers
  • Normal one-stage FVIII แต่ bleeding phenotype

8. Differential Diagnosis (Must exclude before BDUC)

Condition

Key distinguishing feature

VWD

VWF activity

Platelet function disorder

Abnormal aggregometry

Mild hemophilia

factor activity

Ehlers-Danlos syndrome

Hypermobile joints, skin fragility

HHT

Telangiectasia + AVM

Scurvy

Low vitamin C

Rare factor deficiency (XIII)

Normal PT/aPTT


9. Diagnosis Summary (Clinical definition)

วินิจฉัย BDUC เมื่อ:

1.       Positive bleeding phenotype (BAT + history)

2.       Normal:

o   CBC/platelets

o   PT/aPTT/fibrinogen

o   VWD testing

o   Factor VIII/IX/XI

o   Platelet function testing

3.       Excluded secondary causes

4.       No identifiable specific disorder


10. Management Principles (Evidence-limited but practical)

10.1 General bleeding risk reduction

  • Avoid NSAIDs/antiplatelets (ถ้าไม่จำเป็น)
  • Limit alcohol
  • Trauma prevention
  • Medical alert documentation
  • Pre-procedure communication (critical)

10.2 Iron deficiency surveillance (standard care)

Recommended:

  • CBC + ferritin annually (especially menstruating patients)
  • Treat early iron deficiency
  • IV iron if severe blood loss

11. Perioperative Management (High clinical relevance)

General strategy:

  • Consult hematology/hemostasis expert
  • Avoid neuraxial anesthesia (if possible)
  • Multidisciplinary planning (surgeon + anesthesia)

Pharmacologic prophylaxis:

1.       Tranexamic acid (TXA) – first-line

2.       ± Desmopressin (DDAVP)

3.       Platelet transfusion (severe cases)

Combination therapy often used in high-risk surgery

⚠️ No reliable lab marker to monitor response


12. Heavy Menstrual Bleeding (Most common scenario)

ต้อง exclude structural causes (PALM-COEIN) ก่อน

Treatment options:

  • TXA (intermittent during menses)
  • DDAVP during menses
  • Hormonal therapy (OCP, LNG-IUS)
  • Combination therapy if refractory
  • Endometrial ablation / hysterectomy (selected, no fertility plan)

13. Pregnancy & Delivery (Important for OB/ER)

Risk: Postpartum hemorrhage (PPH)

Management:

  • Avoid forceps/instrumental delivery if possible
  • TXA during labor (e.g., 1 g IV/PO)
  • Close PPH monitoring
  • Platelet transfusion / fibrinogen correction if bleeding
  • Vaginal delivery preferred unless obstetric indication for C/S

TXA appears safe (extrapolated WOMAN trial data)


14. When to Refer Hemostasis Specialist

  • Unexplained excessive bleeding
  • Planned major surgery
  • Pregnancy with bleeding history
  • Recurrent transfusion-requiring bleeding
  • Diagnostic uncertainty (possible VWD, platelet disorder, rare factor deficiency)

15. High-yield Clinical Pearls (Board + Practice)

  • BDUC = diagnosis of exclusion
  • Up to 2/3 of referred bleeding patients end as BDUC
  • Heavy menstrual bleeding = most common presentation
  • Normal labs normal hemostasis
  • Iron deficiency is a key morbidity
  • TXA = cornerstone therapy in procedures and HMB
  • Factor XIII deficiency & hyperfibrinolysis are common missed diagnoses
  • Always exclude VWD before labeling BDUC

ไม่มีความคิดเห็น:

แสดงความคิดเห็น